We report a case of eruptive unilateral angiokeratomas with no underlying vascular abnormality. To our knowledge, only 1 other case report of unilateral eruptive angiokeratomas has been reported, and that case was isolated to the scrotum with an underlying vascular defect.1 Other reports of eruptive angiokeratomas associated with cerebral hemangiomas and trauma have been documented, but none of these cases were unilateral.2-5