A 30-year-old man had involuntary orofaciolingual movements for 7 years and unsteady gait for 2 months. At age 23 years, he began experiencing involuntary orofaciolingual movements and vocalizations. At age 27 years, he developed dysphagia, dysarthria, and involuntary tongue- and lip-biting. This oral dyskinesias worsened while eating. However, a handkerchief in the mouth markedly reduced involuntary tongue-biting and mouth movements. No neuropsychiatric symptoms or seizures were exhibited.